A Rare Case of Primary Adrenal Epithelioid Angiosarcoma

Komson Wannasai; Puwitch Charoenchue; Sunhawit Junrungsee; Chanakrit Boonplod; Kornkanok Sukpan

doi:10.12659/AJCR.939397

29 May 2023 : Case report Thailand

A Rare Case of Primary Adrenal Epithelioid Angiosarcoma

Challenging differential diagnosis, Rare disease, Educational Purpose (only if useful for a systematic review or synthesis)

Komson Wannasai

^1ABCDEFG*, Puwitch Charoenchue

^2BDF, Sunhawit Junrungsee^3B, Chanakrit Boonplod

^4BEF, Kornkanok Sukpan^1D

DOI: 10.12659/AJCR.939397

Am J Case Rep 2023; 24:e939397

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Background Case Report Discussion Conclusions References:

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Table 2. Reported cases of primary adrenal epithelioid angiosarcoma.

Author	Pub. Year	Age (y)	Sex	Side	Size (cm)	Presentation
Kareti et al []⁹	1988	54	Male	Left	6.0	Left upper quadrant abdominal pain
Yang et al [] (1)⁶	2018	60	Male	Left	6.5	High blood pressure
Yang et al [] (2)⁶	2018	60	Male	Left	8.0	Severe pain in left lumbar region
Wei et al []¹⁰	2021	51	Male	Left	4.0	Lower back pain
Livaditou et al []¹⁴	1991	59	Male	Right	7.0	Right upper quadrant pain
Li et al []¹³	2017	59	Male	Left	5.4	Left flank pain
Imran et al []¹⁹	2020	38	Female	Right	8.0	Hemoptysis
Bosco et al []²⁴	1991	54	Female	Right	6.0	Fatigue
Croitoru et al []²⁵	2001	63	Male	Left	3.0	Incidental finding
Ben-Izhak et al []²⁶	1992	41	Male	Right	10.0	Epigastric discomfort
Lepoutre-Lussey et al []³³	2012	35	Male	Right	6.0	Polyuria and hypertension
Pasqual et al []²¹	2002	70	Female	Right	5.0	Abdominal pain
Rodríguez-Pinilla et al []¹¹	2002	61	Male	Right	12.0	Abdominal pain
Criscuolo et al []¹²	2013	68	Male	Left	7.0	Pain in left thorax
Antao et al []⁸	2019	58	Male	Left	17.5	Left-sided abdominal pain
Sung et al []²²	2013	42	Male	Right	14.0	Right flank pain
N/A – data not available or no information in the article.
Author	Management	Chemotherapy	Radiotherapy	Outcome
Kareti et al []⁹	Left adrenalectomy with en bloc resection	None	None	Free of tumor
Yang et al [] (1)⁶	Laparoscopic left adrenalectomy	None	None	Alive
Yang et al [] (2)⁶	Left adrenalectomy, left nephrectomy, and splenectomy	None	None	Died of disease
Wei et al []¹⁰	Retroperitoneal laparoscopic resection of the left adrenal tumor	Liposomal doxorubicin and paclitaxel	None	Complete response
Livaditou et al []¹⁴	Adrenalectomy with nephrectomy	None	None	Died 8 days after operation
Li et al []¹³	Left laparoscopic adrenalectomy	N/A	N/A	Followup at 6 months after surgery
Imran et al []¹⁹	Right adrenalectomy	Paclitaxel	N/A	Ongoing chemotherapy
Bosco et al []²⁴	Right adrenalectomy	N/A	N/A	No recurrence
Croitoru et al []²⁵	Left adrenalectomy	N/A	N/A	N/A
Ben-Izhak et al []²⁶	Laparotomy	N/A	Yes	Free of disease
Lepoutre-Lussey et al []³³	Right laparoscopic adrenalectomy	Adriamycin/ifosfamide	N/A	No recurrence
Pasqual et al []²¹	Right adrenalectomy	None	N/A	No recurrence at 18 months after treatment
Rodríguez-Pinilla et al []¹¹	En bloc resection of tumor	None	None	No recurrence at 3 years after treatment
Criscuolo et al []¹²	Laparoscopic ablation	Anthracycline	Yes	Died due to cachexia
Antao et al []⁸	Left adrenalectomy, left nephrectomy, splenectomy, partial gastrectomy, and distal pancreatectomy	Paclitaxel, doxorubicin, carboplatin, etoposide-doxorubicin mitotane	N/A	Died due to disease progression and complications
Sung et al []²²	Right adrenalectomy and right nephrectomy	None	Yes	N/A
N/A – data not available or no information in the article.

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A Rare Case of Primary Adrenal Epithelioid Angiosarcoma

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